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Genomic newborn screening: ICoNS v0.11 ABCC8 Zornitza Stark Marked gene: ABCC8 as ready
Genomic newborn screening: ICoNS v0.11 ABCC8 Zornitza Stark Gene: abcc8 has been classified as Amber List (Moderate Evidence).
Genomic newborn screening: ICoNS v0.11 ABCC8 Zornitza Stark Phenotypes for gene: ABCC8 were changed from Diabetes mellitus, noninsulin-dependent MIM#125853 Diabetes mellitus, permanent neonatal 3 MIM# 618857 AD, AR Diabetes mellitus, transient neonatal 2 MIM#610374 Hyperinsulinemic hypoglycemia, familial, 1 MIM#256450 AD, AR Hypoglycemia of infancy, leucine-sensitive MIM#240800 AD Maturity-onset diabetes of the young, type 12 MIM#621196 AD to Diabetes mellitus, permanent neonatal 3 MIM# 618857
Genomic newborn screening: ICoNS v0.10 ABCC8 Zornitza Stark Classified gene: ABCC8 as Amber List (moderate evidence)
Genomic newborn screening: ICoNS v0.10 ABCC8 Zornitza Stark Gene: abcc8 has been classified as Amber List (Moderate Evidence).
Genomic newborn screening: ICoNS v0.9 ABCC8 Zornitza Stark reviewed gene: ABCC8: Rating: AMBER; Mode of pathogenicity: None; Publications: ; Phenotypes: Diabetes mellitus, permanent neonatal 3 MIM# 618857; Mode of inheritance: MONOALLELIC, autosomal or pseudoautosomal, NOT imprinted
Genomic newborn screening: ICoNS v0.9 ABCC8 Lilian Downie gene: ABCC8 was added
gene: ABCC8 was added to Genomic newborn screening: ICoNS. Sources: Expert list
Mode of inheritance for gene: ABCC8 was set to MONOALLELIC, autosomal or pseudoautosomal, NOT imprinted
Publications for gene: ABCC8 were set to PMID: 20301620; 32027066; 20922570; 16885549
Phenotypes for gene: ABCC8 were set to Diabetes mellitus, noninsulin-dependent MIM#125853 Diabetes mellitus, permanent neonatal 3 MIM# 618857 AD, AR Diabetes mellitus, transient neonatal 2 MIM#610374 Hyperinsulinemic hypoglycemia, familial, 1 MIM#256450 AD, AR Hypoglycemia of infancy, leucine-sensitive MIM#240800 AD Maturity-onset diabetes of the young, type 12 MIM#621196 AD
Review for gene: ABCC8 was set to GREEN
Added comment: Gene-disease association:
Curated by ClinGen: definitive for monogenic diabetes
Moderate for pulmonary hypertension.

LOF heterozygous variants cause hyperinsulinism and neonatal hypoglycemia. requires a paternal pathogenic variant and a somatic second hit on the maternal allele. There is no phenotype for an isolated maternal pathogenic variant.

GoF missense variants cause neonatal diabetes mellitus: Clinical manifestations at diagnosis include intrauterine growth restriction (IUGR; a reflection of insulin deficiency in utero), hyperglycemia, glycosuria, osmotic polyuria, severe dehydration, and poor weight gain.: KATP channel unable to close in response to ATP, impairing insulin secretion

Non-molecular confirmatory testing: yes
For hyperinsulinaemic hypoglycaemia: glucose, insulin, free fatty acid levels
For neonatal diabetes: glucose tolerance test, hemoglobin A1C, insulin level, glucose level

NB Ashkenazi founder variants: NP_000343.2:p.Phe1387del or NM_000352.6:c.3989-9G>A.
Finnish founder variants NP_000343.2:p.Val187Asp or NP_000343.2:p.Glu1506Lys.

Treatment: as per rx-genes
For hyperinsulinaemic hypoglycaemia: Diazoxide, somatostatin analogs, nifedipine, glucagon, IGF-1, glucocorticoids, growth hormone, pancreatic resection, mTOR inhibitors, GLP-1 receptor antagonists, sirolimus

For neonatal diabetes: Insulin, glibenclamide (Sulfonylurea), oral pancreatic enzymes,

Not included by GUARDIAN ?reason ?variable phenotypes, some are adult onset, would need to make variant level decisions on reporting

Variable expression - variants can be inherited and cause T2DM in a parent

Not included in newborn screening currently
Sources: Expert list