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Congenital anomalies of the kidney and urinary tract (CAKUT) v1.5 CHAF1A Lucy Spencer changed review comment from: PMID 39333427 reports 8 individuals from 6 families with oculoauriculovertebral spectrum and heterozygous variants in CHAF1A- 2 canonical splice and 4 PTC. 5 of the variants were de novo (1 of which was then inherited by the probands affected children) and 1 was inherited from a healthy father. all variants were absent from gnomad and the gene is constrained for LOF variants.

Cleft lip/plate was observed in one individual
Sources: Literature; to: PMID 39333427 reports 8 individuals from 6 families with oculoauriculovertebral spectrum and heterozygous variants in CHAF1A- 2 canonical splice and 4 PTC. 5 of the variants were de novo (1 of which was then inherited by the probands affected children) and 1 was inherited from a healthy father. all variants were absent from gnomad and the gene is constrained for LOF variants.

2 individuals had unilateral renal agenesis and vesicoureteral reflux or fused pelvic kidneys
Sources: Literature
Congenital anomalies of the kidney and urinary tract (CAKUT) v1.5 Lucy Spencer Copied gene CHAF1A from panel Clefting disorders
Congenital anomalies of the kidney and urinary tract (CAKUT) v1.5 CHAF1A Lucy Spencer gene: CHAF1A was added
gene: CHAF1A was added to Congenital anomalies of the kidney and urinary tract (CAKUT). Sources: Expert Review Amber,Literature,Literature
Mode of inheritance for gene: CHAF1A was set to MONOALLELIC, autosomal or pseudoautosomal, NOT imprinted
Publications for gene: CHAF1A were set to 39333427
Phenotypes for gene: CHAF1A were set to oculoauriculovertebral spectrum with radial defects MONDO:0007712, CHAF1A-related