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Mendeliome v1.3940 CRIM1 Zornitza Stark Marked gene: CRIM1 as ready
Mendeliome v1.3940 CRIM1 Zornitza Stark Gene: crim1 has been classified as Amber List (Moderate Evidence).
Mendeliome v1.3940 CRIM1 Zornitza Stark Classified gene: CRIM1 as Amber List (moderate evidence)
Mendeliome v1.3940 CRIM1 Zornitza Stark Gene: crim1 has been classified as Amber List (Moderate Evidence).
Mendeliome v1.3939 CRIM1 Zornitza Stark gene: CRIM1 was added
gene: CRIM1 was added to Mendeliome. Sources: Literature
Mode of inheritance for gene: CRIM1 was set to MONOALLELIC, autosomal or pseudoautosomal, imprinted status unknown
Publications for gene: CRIM1 were set to 40114969; 33418956
Phenotypes for gene: CRIM1 were set to Microphthalmia, MONDO:0021129, CRIM1-related
Review for gene: CRIM1 was set to AMBER
Added comment: PMID 33418956 reports 1 individual, and PMID 40114969 reports 3 individuals from 3 families, all with heterozygous loss‑of‑function CRIM1 variants causing colobomatous macropthalmia with microcornea (MACOM) in an autosomal dominant pattern. Segregation is demonstrated across multiple affected relatives, and mouse and zebrafish loss‑of‑function models recapitulate the ocular phenotype, supporting haploinsufficiency as the disease mechanism. However, three of the variants are deletions of various sizes and one of the variants is present in gnomAD.
Sources: Literature