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Genomic newborn screening: BabyScreen+ v1.147 CTU2 Sinead OSullivan gene: CTU2 was added
gene: CTU2 was added to Genomic newborn screening: BabyScreen+. Sources: Literature
Mode of inheritance for gene: CTU2 was set to BIALLELIC, autosomal or pseudoautosomal
Publications for gene: CTU2 were set to PMID: 31301155; 27480277; 26633546
Phenotypes for gene: CTU2 were set to global developmental delay; microcephaly; growth restriction; dysmorphism; renal agenesis; congenital heart defects, epilepsy, microphthalmia; coloboma
Review for gene: CTU2 was set to GREEN
Added comment: PMID: 26633546
- 3 consanguineous families all with the same splice variant (NM_001012762.1:c.873G>A). Assumed to be founder variant
- all had microcephaly but measurements were not provided

PMID: 27480277
- 2 additional patients from an extended consanguineous family with the same variant as above
- Patient 1: head circumference of -3.5SD at birth, not growing
- Patient 2: head circumference of -4.3 SD

PMID: 31301155
- 5 new patients with microcephaly (no measurements provided)
- 3x PTVs and 1x missense

PMID: 38348206
- 1 new patient with microcephaly, dysmorphism, ambiguous genitalia and atrial septal defect
- From the consanguineous family stated above with the splice site founder variant (NM_001012762.1:c.873G>A)
Sources: Literature