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Mendeliome v1.3482 EIPR1 Zornitza Stark Marked gene: EIPR1 as ready
Mendeliome v1.3482 EIPR1 Zornitza Stark Gene: eipr1 has been classified as Green List (High Evidence).
Mendeliome v1.3482 EIPR1 Zornitza Stark Classified gene: EIPR1 as Green List (high evidence)
Mendeliome v1.3482 EIPR1 Zornitza Stark Gene: eipr1 has been classified as Green List (High Evidence).
Mendeliome v1.3479 EIPR1 Thomas Cloney gene: EIPR1 was added
gene: EIPR1 was added to Mendeliome. Sources: Literature
Mode of inheritance for gene: EIPR1 was set to BIALLELIC, autosomal or pseudoautosomal
Publications for gene: EIPR1 were set to 41058046
Phenotypes for gene: EIPR1 were set to Mendelian neurodevelopmental disorder MONDO:0100500, EIPR1-related
Penetrance for gene: EIPR1 were set to unknown
Review for gene: EIPR1 was set to GREEN
Added comment: Report of 8 individuals from 6 unrelated consanguinous families with homozygous EIPR1 variants (5 different variants).
Phenotype: All had global developmental delay (range of severity), with significant motor delay (5/8 never attained walking). Neurological manifestations: 2/8 Hypotonia, 4/8 had spasticity. 5/8 had microcepahly. MRI Brain abnormalities included: delayed myelination, hypoplasia of the corpus callosum, mild cerebellar atrophy, dysmorphic lateral ventricles. (Limited phenotypic information in pre-print - all in supplementary data)
Functional data: In vitro functional work show reduced protrien levels and interaction with EARP and GARP; and in vivo zebrafish models with knowckout of EIPR1 result in neurodevelopmental and locomotor defects
Sources: Literature