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Pulmonary Fibrosis_Interstitial Lung Disease v0.190 IFIH1 Zornitza Stark Marked gene: IFIH1 as ready
Pulmonary Fibrosis_Interstitial Lung Disease v0.190 IFIH1 Zornitza Stark Gene: ifih1 has been classified as Amber List (Moderate Evidence).
Pulmonary Fibrosis_Interstitial Lung Disease v0.190 IFIH1 Zornitza Stark Classified gene: IFIH1 as Amber List (moderate evidence)
Pulmonary Fibrosis_Interstitial Lung Disease v0.190 IFIH1 Zornitza Stark Gene: ifih1 has been classified as Amber List (Moderate Evidence).
Pulmonary Fibrosis_Interstitial Lung Disease v0.189 IFIH1 Zornitza Stark gene: IFIH1 was added
gene: IFIH1 was added to Pulmonary Fibrosis_Interstitial Lung Disease. Sources: Literature
Mode of inheritance for gene: IFIH1 was set to MONOALLELIC, autosomal or pseudoautosomal, imprinted status unknown
Publications for gene: IFIH1 were set to 37126154; 32508843
Phenotypes for gene: IFIH1 were set to Aicardi-Goutieres syndrome 7, MIM#615846
Review for gene: IFIH1 was set to AMBER
Added comment: PMID 32508843 reports an individual with a heterozygous gain-of-function IFIH1 p.R779H variant causing Aicardi‑Goutières syndrome with interstitial lung disease, psoriasis and pulmonary hypertension; PMID 37126154 reports a second individual with a de novo heterozygous gain-of-function IFIH1 variant causing infantile lethal interstitial lung disease. This may be be a rare but significant manifestation of AGS.
Sources: Literature