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Mendeliome v2.340 PPIL4 Zornitza Stark Marked gene: PPIL4 as ready
Mendeliome v2.340 PPIL4 Zornitza Stark Gene: ppil4 has been classified as Amber List (Moderate Evidence).
Mendeliome v2.333 PPIL4 Sangavi Sivagnanasundram Classified gene: PPIL4 as Amber List (moderate evidence)
Mendeliome v2.333 PPIL4 Sangavi Sivagnanasundram Gene: ppil4 has been classified as Amber List (Moderate Evidence).
Mendeliome v2.320 PPIL4 Sangavi Sivagnanasundram gene: PPIL4 was added
gene: PPIL4 was added to Mendeliome. Sources: Literature
Mode of inheritance for gene: PPIL4 was set to MONOALLELIC, autosomal or pseudoautosomal, NOT imprinted
Publications for gene: PPIL4 were set to 34887573
Phenotypes for gene: PPIL4 were set to PPIL4-related intracranial saccular aneurysm MONDO:0016483
Review for gene: PPIL4 was set to AMBER
Added comment: PMID 34887573 reports 5 unrelated families with 5 different heterozygous PPIL4 variants presenting with adult‑onset intracranial saccular aneurysm, a risk factor for subarachnoid haemorrhage.
The variants are present in gnomAD v4.1, two are a bit common for AD AF.
There are no pathogenic variants reported in ClinVar at this stage. The gene is not constraint for LoF however the authors of this are hypothesising haploinsufficiency as the mechanism of disease.
Rated AMBER given the uncertainty of the GDA and functional evidence.
Sources: Literature
Mendeliome v2.0 IL4 Gene migrated from ENSG00000113520 to ENSG00000113520 (gene set migration)
Mendeliome v0.11490 IL4 Zornitza Stark Marked gene: IL4 as ready
Mendeliome v0.11490 IL4 Zornitza Stark Gene: il4 has been classified as Red List (Low Evidence).
Mendeliome v0.11490 IL4 Zornitza Stark Classified gene: IL4 as Red List (low evidence)
Mendeliome v0.11490 IL4 Zornitza Stark Gene: il4 has been classified as Red List (Low Evidence).
Mendeliome v0.11489 IL4 Zornitza Stark reviewed gene: IL4: Rating: RED; Mode of pathogenicity: None; Publications: ; Phenotypes: ; Mode of inheritance: None
Mendeliome v0.0 IL4 Zornitza Stark gene: IL4 was added
gene: IL4 was added to Mendeliome_VCGS. Sources: Expert Review Green,Victorian Clinical Genetics Services
Mode of inheritance for gene: IL4 was set to Unknown