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Ataxia v2.73 INPP4A Bryony Thompson Marked gene: INPP4A as ready
Ataxia v2.73 INPP4A Bryony Thompson Gene: inpp4a has been classified as Green List (High Evidence).
Ataxia v2.73 INPP4A Bryony Thompson Classified gene: INPP4A as Green List (high evidence)
Ataxia v2.73 INPP4A Bryony Thompson Gene: inpp4a has been classified as Green List (High Evidence).
Ataxia v2.72 INPP4A Bryony Thompson gene: INPP4A was added
gene: INPP4A was added to Ataxia. Sources: Literature
Mode of inheritance for gene: INPP4A was set to BIALLELIC, autosomal or pseudoautosomal
Publications for gene: INPP4A were set to 39315527
Phenotypes for gene: INPP4A were set to Neurodevelopmental disorder, MONDO:0700092
Review for gene: INPP4A was set to GREEN
Added comment: PMID 39315527 reports 21 affected individuals from 12 families (9 independent) with biallelic loss‑of‑function INPP4A variants causing a neurodevelopmental disorder characterised by global developmental delay, severe intellectual disability, microcephaly, limb weakness, cerebellar signs and prominent ataxia. Multiple unrelated families (≥3) harbour qualifying LoF variants, and mouse knockout models recapitulate the phenotype.
Sources: Literature