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Mendeliome v2.93 LHX1 Zornitza Stark Marked gene: LHX1 as ready
Mendeliome v2.93 LHX1 Zornitza Stark Gene: lhx1 has been classified as Green List (High Evidence).
Mendeliome v2.93 LHX1 Zornitza Stark Classified gene: LHX1 as Green List (high evidence)
Mendeliome v2.93 LHX1 Zornitza Stark Gene: lhx1 has been classified as Green List (High Evidence).
Mendeliome v2.92 LHX1 Zornitza Stark gene: LHX1 was added
gene: LHX1 was added to Mendeliome. Sources: Literature
Mode of inheritance for gene: LHX1 was set to MONOALLELIC, autosomal or pseudoautosomal, NOT imprinted
Publications for gene: LHX1 were set to 41632294; 29527097; 28061432
Phenotypes for gene: LHX1 were set to Mayer-Rokitansky-Kuster-Hauser syndrome, MONDO:0017771, LHX1-related
Review for gene: LHX1 was set to GREEN
Added comment: PMID 41632294, PMID 29527097 and PMID 28061432 collectively report six MRKH families with heterozygous LHX1 variants—three low‑level mosaic deletions (c.676_841del), one frameshift truncation, and a missense variant (c.G1108A (p.A370T)) that reduces transcriptional activity. The deletions are de novo mosaic, the frameshift is a predicted null allele, and the missense variant shows functional impairment in a luciferase assay. A mouse Lhx1 knockout reproduces the phenotype.
Sources: Literature