Activity

Filter

Cancel
Date Panel Item Activity
5 actions
Ataxia v2.97 LRSAM1 Bryony Thompson Marked gene: LRSAM1 as ready
Ataxia v2.97 LRSAM1 Bryony Thompson Gene: lrsam1 has been classified as Green List (High Evidence).
Ataxia v2.97 LRSAM1 Bryony Thompson Classified gene: LRSAM1 as Green List (high evidence)
Ataxia v2.97 LRSAM1 Bryony Thompson Gene: lrsam1 has been classified as Green List (High Evidence).
Ataxia v2.96 LRSAM1 Bryony Thompson gene: LRSAM1 was added
gene: LRSAM1 was added to Ataxia. Sources: Literature
Mode of inheritance for gene: LRSAM1 was set to MONOALLELIC, autosomal or pseudoautosomal, NOT imprinted
Publications for gene: LRSAM1 were set to 30996334
Phenotypes for gene: LRSAM1 were set to Charcot-Marie-Tooth disease axonal type 2P, MONDO:0013753
Review for gene: LRSAM1 was set to GREEN
Added comment: PMID 30996334 reports 72 individuals from 8 families (5 independent) with heterozygous in‑frame LRSAM1 variants presenting with adult‑onset sensory ataxia, neuropathic pain and length‑dependent sensory loss. This dominant‑negative mechanism causes Charcot‑Marie‑Tooth disease type 2P, an ataxic neuropathy that falls within the Ataxia panel’s scope of disorders featuring prominent ataxia.
Sources: Literature