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Mitochondrial disease v0.1035 MT-RNR1 Zornitza Stark Phenotypes for gene: MT-RNR1 were changed from Deafness; Cardiomyopathy to Mitochondrial disease (MONDO:0044970), MT-RNR1-related
Mitochondrial disease v0.1034 MT-RNR1 Zornitza Stark Publications for gene: MT-RNR1 were set to 20301595
Mitochondrial disease v0.1033 MT-RNR1 Zornitza Stark edited their review of gene: MT-RNR1: Added comment: DEFINITIVE by ClinGen.

Over 70 affected individuals reported. Two variants, m.1555A>G and m.1494C>T, are recurrent.

These variants are predominantly associated with hearing loss. Some individuals with this variants have normal hearing, others have hearing loss following aminoglycoside exposure, and others have hearing loss and no known aminoglycoside exposure. Age of onset of hearing loss ranged from infancy (after aminoglycoside exposure) to adulthood. Hearing loss has been reported to be variable, stable in some individuals and progressive in others.

Additional variants in this gene have been reported to be associated with primary mitochondrial disease, however insufficient clinical detail was provided and/or there was a lack of comprehensive analyses excluding other causes, therefore these additional variants were not included in the ClinGen curation (m.827A>G – PMIDs: 16650816, 16782057, 18261986; m.961delTinsC - PMIDs: 7550368, 10326749; m.1027A>G – PMIDs: 23328039, 21205314, 20100600; m.1095T>C – PMIDs: 11313749, 11079536, 15637703).; Changed publications: 7698299, 16380089, 12920080, 24252789, 9490575, 8285309, 9040738, 7689389; Changed phenotypes: Mitochondrial disease (MONDO:0044970), MT-RNR1-related
Mitochondrial disease v0.622 MT-RNR1 Zornitza Stark Publications for gene: MT-RNR1 were set to
Mitochondrial disease v0.621 MT-RNR1 Chern Lim reviewed gene: MT-RNR1: Rating: GREEN; Mode of pathogenicity: None; Publications: 20301595; Phenotypes: ; Mode of inheritance: MITOCHONDRIAL; Current diagnostic: yes
Mitochondrial disease v0.430 MT-RNR1 Zornitza Stark Tag mtDNA tag was added to gene: MT-RNR1.
Mitochondrial disease v0.387 MT-RNR1 Zornitza Stark Marked gene: MT-RNR1 as ready
Mitochondrial disease v0.387 MT-RNR1 Zornitza Stark Gene: mt-rnr1 has been classified as Green List (High Evidence).
Mitochondrial disease v0.387 MT-RNR1 Zornitza Stark Classified gene: MT-RNR1 as Green List (high evidence)
Mitochondrial disease v0.387 MT-RNR1 Zornitza Stark Gene: mt-rnr1 has been classified as Green List (High Evidence).
Mitochondrial disease v0.386 MT-RNR1 Zornitza Stark gene: MT-RNR1 was added
gene: MT-RNR1 was added to Mitochondrial disease. Sources: Expert list
Mode of inheritance for gene gene: MT-RNR1 was set to MITOCHONDRIAL
Phenotypes for gene: MT-RNR1 were set to Deafness; Cardiomyopathy
Review for gene: MT-RNR1 was set to GREEN
Added comment: Sources: Expert list