Activity

Filter

Cancel
Date Panel Item Activity
5 actions
Ataxia v2.150 NARS1 Bryony Thompson Marked gene: NARS1 as ready
Ataxia v2.150 NARS1 Bryony Thompson Gene: nars1 has been classified as Green List (High Evidence).
Ataxia v2.150 NARS1 Bryony Thompson Classified gene: NARS1 as Green List (high evidence)
Ataxia v2.150 NARS1 Bryony Thompson Gene: nars1 has been classified as Green List (High Evidence).
Ataxia v2.149 NARS1 Bryony Thompson gene: NARS1 was added
gene: NARS1 was added to Ataxia. Sources: Literature
Mode of inheritance for gene: NARS1 was set to BOTH monoallelic and biallelic, autosomal or pseudoautosomal
Publications for gene: NARS1 were set to 38495304; 32738225
Phenotypes for gene: NARS1 were set to Neurodevelopmental disorder, MONDO:0700092; neurodevelopmental disorder with microcephaly, impaired language, and gait abnormalities, MONDO:0100348; neurodevelopmental disorder with microcephaly, impaired language, epilepsy, and gait abnormalities, MONDO:0030837
Review for gene: NARS1 was set to GREEN
Added comment: Both dominant and recessive NARS1‑related neurodevelopmental disorders feature ataxia, aligning them with the Ataxia panel's scope.
Manole2020 reports eight unrelated families with de novo heterozygous NARS1 variants causing a dominant neurodevelopmental disorder with microcephaly, seizures and gait ataxia (toxic gain‑of‑function).
Beijer2024 describes a de novo in‑frame deletion in a single family causing a dominant neurodevelopmental disorder characterised by cerebellar ataxia, pyramidal signs, developmental delay, intellectual disability and peripheral neuropathy.
Manole2020 also identifies thirteen unrelated families with biallelic NARS1 variants resulting in a recessive neurodevelopmental disorder with microcephaly, impaired language and gait ataxia (partial loss‑of‑function).
Sources: Literature