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Mendeliome v1.3868 NUBP2 Zornitza Stark Marked gene: NUBP2 as ready
Mendeliome v1.3868 NUBP2 Zornitza Stark Gene: nubp2 has been classified as Amber List (Moderate Evidence).
Mendeliome v1.3868 NUBP2 Zornitza Stark Classified gene: NUBP2 as Amber List (moderate evidence)
Mendeliome v1.3868 NUBP2 Zornitza Stark Gene: nubp2 has been classified as Amber List (Moderate Evidence).
Mendeliome v1.3867 NUBP2 Zornitza Stark gene: NUBP2 was added
gene: NUBP2 was added to Mendeliome. Sources: Literature
Mode of inheritance for gene: NUBP2 was set to BIALLELIC, autosomal or pseudoautosomal
Publications for gene: NUBP2 were set to 39867373
Phenotypes for gene: NUBP2 were set to Neurodevelopmental disorder, MONDO:0700092
Review for gene: NUBP2 was set to AMBER
Added comment: PMID 39867373 reports 2 individuals from 2 unrelated families with biallelic missense variants in NUBP2 presenting with congenital primary microcephaly, intrauterine growth restriction, severe joint contractures and facial dysmorphism. A forebrain‑specific conditional Nubp2 knockout mouse recapitulates the severe microcephaly, and rescue assays show patient alleles fail to restore growth, supporting a loss‑of‑function mechanism.

Preprint.
Sources: Literature