Activity

Filter

Cancel
Date Panel Item Activity
14 actions
Aminoacidopathy v1.138 PPM1K Zornitza Stark edited their review of gene: PPM1K: Added comment: Additional individual reported in PMID 40047138 noted. However, variant is homozygous missense and thus a VOUS.; Changed rating: AMBER; Changed publications: 23086801, 40047138
Aminoacidopathy v1.138 PPM1K Andrew Coventry changed review comment from: New literature identifies 8 yo male child presenting with mild dysmorphic features, delayed speech, relative microcephaly, and overweight, all considered familial phenotypic traits.
Laboratory findings revealed mildly elevated plasma branched-chain amino acids, mild lactic acidemia, and a slight increase in urinary keto acids. Testing identified homozygous missense variant in PPM1K - c.925A>G p.(Ile309Val). No functional studies conducted. In silico predicts residual to have destabilising impact on protein.
3 individuals now reported in literature with mild findings related to MSUD BCAA levels. Adequate evidence to include in panel?; to: New literature identifies 8 yo male child presenting with mild dysmorphic features, delayed speech, relative microcephaly, and overweight, all considered familial phenotypic traits.
Laboratory findings revealed mildly elevated plasma branched-chain amino acids, mild lactic acidemia, and a slight increase in urinary keto acids. Testing identified homozygous missense variant in PPM1K - c.925A>G p.(Ile309Val). No functional studies conducted. In silico predicts AA substitution to have destabilising impact on protein.
3 individuals now reported in literature with mild findings related to MSUD BCAA levels. Adequate evidence to include in panel?
Aminoacidopathy v1.138 PPM1K Andrew Coventry reviewed gene: PPM1K: Rating: AMBER; Mode of pathogenicity: None; Publications: 36706222, 23086801, 40047138; Phenotypes: Maple syrup urine disease, mild variant, MIM#615135; Mode of inheritance: BIALLELIC, autosomal or pseudoautosomal
Aminoacidopathy v1.4 PPM1K Zornitza Stark Phenotypes for gene: PPM1K were changed from maple syrup urine disease, mild variant MONDO:0014057 to Maple syrup urine disease, mild variant MONDO:0014057
Aminoacidopathy v1.3 PPM1K Zornitza Stark Publications for gene: PPM1K were set to 29152456; 23086801
Aminoacidopathy v1.2 PPM1K Zornitza Stark Classified gene: PPM1K as Amber List (moderate evidence)
Aminoacidopathy v1.2 PPM1K Zornitza Stark Gene: ppm1k has been classified as Amber List (Moderate Evidence).
Aminoacidopathy v1.1 PPM1K Suliman Khan reviewed gene: PPM1K: Rating: AMBER; Mode of pathogenicity: None; Publications: PMID: 36706222; Phenotypes: Maple syrup urine disease (MSUD); Mode of inheritance: BIALLELIC, autosomal or pseudoautosomal
Aminoacidopathy v0.3 PPM1K Bryony Thompson Marked gene: PPM1K as ready
Aminoacidopathy v0.3 PPM1K Bryony Thompson Gene: ppm1k has been classified as Red List (Low Evidence).
Aminoacidopathy v0.3 PPM1K Bryony Thompson Publications for gene: PPM1K were set to 29152456
Aminoacidopathy v0.2 PPM1K Bryony Thompson Classified gene: PPM1K as Red List (low evidence)
Aminoacidopathy v0.2 PPM1K Bryony Thompson Gene: ppm1k has been classified as Red List (Low Evidence).
Aminoacidopathy v0.0 PPM1K Bryony Thompson gene: PPM1K was added
gene: PPM1K was added to Disorders of branched chain amino acid metabolism. Sources: Expert Review Green
Mode of inheritance for gene: PPM1K was set to BIALLELIC, autosomal or pseudoautosomal
Publications for gene: PPM1K were set to 29152456
Phenotypes for gene: PPM1K were set to maple syrup urine disease, mild variant MONDO:0014057