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Mendeliome v1.4876 PTCHD3 Chirag Patel Marked gene: PTCHD3 as ready
Mendeliome v1.4876 PTCHD3 Chirag Patel Gene: ptchd3 has been classified as Red List (Low Evidence).
Mendeliome v1.4876 PTCHD3 Chirag Patel Phenotypes for gene: PTCHD3 were changed from Syndromic disease, MONDO:0002254 to Nevoid basal cell carcinoma syndrome, MONDO:0007187
Mendeliome v1.4875 PTCHD3 Chirag Patel gene: PTCHD3 was added
gene: PTCHD3 was added to Mendeliome. Sources: Literature
Mode of inheritance for gene: PTCHD3 was set to MONOALLELIC, autosomal or pseudoautosomal, NOT imprinted
Publications for gene: PTCHD3 were set to 41848310
Phenotypes for gene: PTCHD3 were set to Syndromic disease, MONDO:0002254
Review for gene: PTCHD3 was set to RED
Added comment: 2 individuals from 1 unrelated family (father-daughter) with a monoallelic variant in PTCHD3 presenting with Basal Cell Nevus Syndrome (BCNS). Clinical features include multiple odontogenic keratocysts, facial pigmented nevi, hypertelorism, and frontal-parietal bone protrusion. The authors propose the variant activates the Hedgehog pathway, supported by molecular docking simulations and increased expression of matrix metalloproteinases in patient-derived fibroblasts.
Sources: Literature