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Mendeliome v2.240 BIRC3 Zornitza Stark gene: BIRC3 was added
gene: BIRC3 was added to Mendeliome. Sources: Literature
Mode of inheritance for gene: BIRC3 was set to BOTH monoallelic and biallelic, autosomal or pseudoautosomal
Publications for gene: BIRC3 were set to 42335979
Phenotypes for gene: BIRC3 were set to Inborn error of immunity, MONDO:0003778
Review for gene: BIRC3 was set to AMBER
Added comment: BIRC3 encodes cellular inhibitor of apoptosis protein 2 (cIAP2), a regulator of TNF signalling. Association with Crohn's disease:
Monoallelic disease -- 8 individuals from 7 families with heterozygous BIRC3 variants (including 1 de novo and 2 recurrent p.H312Y families; inheritance of rest not determined); functional assays show impaired RIPK1 ubiquitylation and increased epithelial cell death.
Biallelic disease (infancy onset) – 6 individuals from 3 consanguineous families with homozygous loss-of-function BIRC3 variants; patient‑cell and animal models recapitulate the disease phenotype.

Two MOIs proposed, several of the variants not segregated, others homozygous, hence Amber rating overall.
Sources: Literature
Mendeliome v2.0 RIPK1 Gene migrated from ENSG00000137275 to ENSG00000137275 (gene set migration)
Mendeliome v1.3446 RIPK1 Lucy Spencer reviewed gene: RIPK1: Rating: ; Mode of pathogenicity: None; Publications: ; Phenotypes: Autoinflammation with episodic fever and lymphadenopathy MIM#618852; Mode of inheritance: None
Mendeliome v0.2680 RIPK1 Zornitza Stark Marked gene: RIPK1 as ready
Mendeliome v0.2680 RIPK1 Zornitza Stark Gene: ripk1 has been classified as Green List (High Evidence).
Mendeliome v0.2680 RIPK1 Zornitza Stark Phenotypes for gene: RIPK1 were changed from to Immunodeficiency 57, MIM#618108
Mendeliome v0.2679 RIPK1 Zornitza Stark Publications for gene: RIPK1 were set to
Mendeliome v0.2678 RIPK1 Zornitza Stark Mode of inheritance for gene: RIPK1 was changed from Unknown to BOTH monoallelic and biallelic, autosomal or pseudoautosomal
Mendeliome v0.2677 RIPK1 Zornitza Stark reviewed gene: RIPK1: Rating: GREEN; Mode of pathogenicity: None; Publications: 30026316, 30591564, 31213653, 31827280; Phenotypes: Immunodeficiency 57, MIM#618108; Mode of inheritance: BOTH monoallelic and biallelic, autosomal or pseudoautosomal
Mendeliome v0.0 RIPK1 Zornitza Stark gene: RIPK1 was added
gene: RIPK1 was added to Mendeliome_VCGS. Sources: Expert Review Green,Victorian Clinical Genetics Services
Mode of inheritance for gene: RIPK1 was set to Unknown