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Mendeliome v1.3882 RNU6-8 Zornitza Stark Marked gene: RNU6-8 as ready
Mendeliome v1.3882 RNU6-8 Zornitza Stark Gene: rnu6-8 has been classified as Green List (High Evidence).
Mendeliome v1.3882 RNU6-8 Zornitza Stark Classified gene: RNU6-8 as Green List (high evidence)
Mendeliome v1.3882 RNU6-8 Zornitza Stark Gene: rnu6-8 has been classified as Green List (High Evidence).
Mendeliome v1.3881 RNU6-8 Zornitza Stark gene: RNU6-8 was added
gene: RNU6-8 was added to Mendeliome. Sources: Literature
Mode of inheritance for gene: RNU6-8 was set to MONOALLELIC, autosomal or pseudoautosomal, imprinted status unknown
Publications for gene: RNU6-8 were set to 39830270
Phenotypes for gene: RNU6-8 were set to Retinitis pigmentosa MONDO:0019200, RNU6-8-related
Review for gene: RNU6-8 was set to GREEN
Added comment: PMID 39830270 reports multiple individuals with a dominant insertion variant (n.55_56insG) in RNU6-8 presenting with autosomal dominant retinitis pigmentosa, adolescent onset and progressive peripheral vision loss. Co‑IP assays demonstrate increased binding of mutant U6 snRNA to SART3 and PRPF31, supporting a dominant‑negative mechanism; both de novo and inherited cases are described. Note multiple RNU6 paralogues.
Sources: Literature