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Ataxia v2.146 SRPK3 Sangavi Sivagnanasundram gene: SRPK3 was added
gene: SRPK3 was added to Ataxia. Sources: Literature
Mode of inheritance for gene: SRPK3 was set to X-LINKED: hemizygous mutation in males, monoallelic mutations in females may cause disease (may be less severe, later onset than males)
Publications for gene: SRPK3 were set to 39073169
Phenotypes for gene: SRPK3 were set to intellectual developmental disorder, X-linked 114, MONDO:0975828
Review for gene: SRPK3 was set to AMBER
Added comment: PMID 39073169 reports two individuals presenting with intellectual disability, agenesis of the corpus callosum, cerebellar atrophy, abnormal eye movements and progressive ataxia and X-linked variants in SRPK3.
One of the variants c.1585G>A:p.Glu529Lys has a FAF of 0.006% in gnomAD v4.1 (96 hets and 32 hemizygotes globally).
Supportive knockout zebrafish models recapitulated the ocular and motor phenotype, including evidence of ataxia.
Sources: Literature