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Cataract v0.601 USP9X Zornitza Stark Marked gene: USP9X as ready
Cataract v0.601 USP9X Zornitza Stark Gene: usp9x has been classified as Green List (High Evidence).
Cataract v0.601 USP9X Zornitza Stark Classified gene: USP9X as Green List (high evidence)
Cataract v0.601 USP9X Zornitza Stark Gene: usp9x has been classified as Green List (High Evidence).
Cataract v0.600 USP9X Zornitza Stark gene: USP9X was added
gene: USP9X was added to Cataract. Sources: Literature
Mode of inheritance for gene: USP9X was set to X-LINKED: hemizygous mutation in males, monoallelic mutations in females may cause disease (may be less severe, later onset than males)
Publications for gene: USP9X were set to 38099911; 37895297
Phenotypes for gene: USP9X were set to Intellectual developmental disorder, X-linked 99, syndromic, female-restricted, MIM# 300968
Review for gene: USP9X was set to GREEN
Added comment: PMID 37895297 reports three unrelated female families with heterozygous loss‑of‑function USP9X variants (splice c.1314+2T>C, nonsense c.121G>T, frameshift c.1603dupA) presenting with Axenfeld–Rieger anomaly, congenital glaucoma, corneal neovascularization and cataract (two cases). PMID 38099911 reports an additional unrelated family with a heterozygous USP9X c.799_802del deletion causing bilateral cataracts, posterior lentiglobus and multiple systemic anomalies.
Sources: Literature