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Mendeliome v2.0 WDHD1 Gene migrated from ENSG00000198554 to ENSG00000198554 (gene set migration)
Mendeliome v1.4805 WDHD1 Zornitza Stark Marked gene: WDHD1 as ready
Mendeliome v1.4805 WDHD1 Zornitza Stark Gene: wdhd1 has been classified as Green List (High Evidence).
Mendeliome v1.4805 WDHD1 Zornitza Stark Classified gene: WDHD1 as Green List (high evidence)
Mendeliome v1.4805 WDHD1 Zornitza Stark Gene: wdhd1 has been classified as Green List (High Evidence).
Mendeliome v1.4744 WDHD1 Achchuthan Shanmugasundram gene: WDHD1 was added
gene: WDHD1 was added to Mendeliome. Sources: Literature
Mode of inheritance for gene: WDHD1 was set to BIALLELIC, autosomal or pseudoautosomal
Publications for gene: WDHD1 were set to 41962535
Phenotypes for gene: WDHD1 were set to microcephalic osteodysplastic primordial dwarfism, MONDO:0000060
Review for gene: WDHD1 was set to GREEN
Added comment: PMID:41962535 (2026) reported the identification of biallelic hypomorphic variants in WDHD1 gene in 17 patients from 14 families with microcephalic primordial dwarfism (MPD) and a broad spectrum of additional abnormalities including acute liver failure. There is also functional evidence available from patient-derived fibroblasts which supports the disease association.
Sources: Literature