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Mendeliome v1.4543 XPOT Zornitza Stark Marked gene: XPOT as ready
Mendeliome v1.4543 XPOT Zornitza Stark Gene: xpot has been classified as Green List (High Evidence).
Mendeliome v1.4543 XPOT Zornitza Stark Classified gene: XPOT as Green List (high evidence)
Mendeliome v1.4543 XPOT Zornitza Stark Gene: xpot has been classified as Green List (High Evidence).
Mendeliome v1.4542 XPOT Zornitza Stark gene: XPOT was added
gene: XPOT was added to Mendeliome. Sources: Literature
preprint tags were added to gene: XPOT.
Mode of inheritance for gene: XPOT was set to BIALLELIC, autosomal or pseudoautosomal
Publications for gene: XPOT were set to 10.64898/2026.01.28.26344748
Phenotypes for gene: XPOT were set to Syndromic disease, MONDO:0002254
Review for gene: XPOT was set to GREEN
Added comment: Preprint by Von Hardenberg et al 2026 reports 8 individuals from 5 unrelated families with biallelic loss‑of‑function XPOT variants presenting with childhood‑onset severe sensorineural hearing loss, recurrent infections/bronchiectasis, developmental delay and growth retardation. Functional studies show absent XPOT protein in patient fibroblasts, reduced TNF‑α translation, and xpot‑deficient zebrafish recapitulating the multisystem phenotype.

All reported variants are homozygous.
Sources: Literature