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Angelman Rett like syndromes v2.2 CHD8 Zornitza Stark Marked gene: CHD8 as ready
Angelman Rett like syndromes v2.2 CHD8 Zornitza Stark Gene: chd8 has been classified as Red List (Low Evidence).
Angelman Rett like syndromes v2.2 CHD8 Zornitza Stark gene: CHD8 was added
gene: CHD8 was added to Angelman Rett like syndromes. Sources: Literature
Mode of inheritance for gene: CHD8 was set to MONOALLELIC, autosomal or pseudoautosomal, NOT imprinted
Publications for gene: CHD8 were set to 40496977
Phenotypes for gene: CHD8 were set to Intellectual developmental disorder with autism and macrocephaly #615032
Review for gene: CHD8 was set to RED
Added comment: Single individual reported with a heterozygous stop-gain variant [NM_001170629.2: c.5017C>T, p.(Arg1673⁣∗)], in the chromodomain-helicase-DNA-binding protein 8 (CHD8) gene. In vitro functional analyses, including Western blots, quantitative reverse transcription polymerase chain reaction (qRT-PCR), and proteomic analyses, demonstrated a significant reduction of the CHD8 transcript and two CHD8 protein isoforms in the proband's skin fibroblasts relative to control fibroblasts. Additionally, proteomic analysis indicated a significant reduction of the MeCP2 protein, indicating a possible molecular link between CHD8 and MeCP2 and thus clinically between IDDAM and RTT.
Sources: Literature