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Intellectual disability syndromic and non-syndromic v2.97 DDX1 chirag patel Marked gene: DDX1 as ready
Intellectual disability syndromic and non-syndromic v2.97 DDX1 chirag patel Gene: ddx1 has been classified as Amber List (Moderate Evidence).
Intellectual disability syndromic and non-syndromic v2.97 DDX1 chirag patel Classified gene: DDX1 as Amber List (moderate evidence)
Intellectual disability syndromic and non-syndromic v2.97 DDX1 chirag patel Gene: ddx1 has been classified as Amber List (Moderate Evidence).
Intellectual disability syndromic and non-syndromic v2.96 DDX1 chirag patel gene: DDX1 was added
gene: DDX1 was added to Intellectual disability syndromic and non-syndromic. Sources: Other
Mode of inheritance for gene: DDX1 was set to MONOALLELIC, autosomal or pseudoautosomal, NOT imprinted
Phenotypes for gene: DDX1 were set to Neurodevelopmental disorder, MONDO:0700092, DDX1-related
Review for gene: DDX1 was set to AMBER
Added comment: ESHG 2026

9 unrelated individuals with 7 different rare heterozygous de novo variants (6 missense, 1 splice) involving conserved residues in critical domains of DDX1 gene. Individuals presented with developmental delay, hypotonia (9/9), distinctive facial gestalt (9/9), behavioral dysregulation (8/9), hand/foot skeletal anomalies (7/9), seizures (4/9), spasticity (4/9), and ataxia (3/9).

DEAD/DExH-box RNA (DDX) helicases are key regulators of RNA metabolism and cellular stress responses, and their dysfunction has been associated with distinct neurodevelopmental syndromes. DDX1 regulates RNA metabolism and genome integrity, and is an essential regulator of cellular responses to genotoxic and environmental stress. In silico analysis predicted all variants decrease protein stability. Patient-derived fibroblasts showed impaired radiation-induced DNA double-strand break repair, defective protection of specific target mRNAs under oxidative stress conditions, increased production of reactive oxygen species, and reduced mitochondrial function.
Sources: Other
Intellectual disability syndromic and non-syndromic v1.360 DDX11 chirag patel Source Genetic Health Queensland was removed from DDX11.
Source ClinGen was added to DDX11.
Phenotypes for gene: DDX11 were changed from Warsaw breakage syndrome, MIM# 613398; MONDO:0013252 to Warsaw breakage syndrome, MONDO:0013252
Publications for gene DDX11 were changed from 20137776, 23033317, 30216658, 30924321, 32855419, 36703504, 26089203 to 20137776, 23033317, 30216658, 30924321, 32855419, 36703504, 26089203
Intellectual disability syndromic and non-syndromic v0.5631 DDX17 Elena Savva Classified gene: DDX17 as Green List (high evidence)
Intellectual disability syndromic and non-syndromic v0.5631 DDX17 Elena Savva Gene: ddx17 has been classified as Green List (High Evidence).
Intellectual disability syndromic and non-syndromic v0.5630 DDX17 Elena Savva Classified gene: DDX17 as Green List (high evidence)
Intellectual disability syndromic and non-syndromic v0.5630 DDX17 Elena Savva Gene: ddx17 has been classified as Green List (High Evidence).
Intellectual disability syndromic and non-syndromic v0.5629 DDX17 Elena Savva Marked gene: DDX17 as ready
Intellectual disability syndromic and non-syndromic v0.5629 DDX17 Elena Savva Gene: ddx17 has been removed from the panel.
Intellectual disability syndromic and non-syndromic v0.5627 DDX17 Melanie Marty gene: DDX17 was added
gene: DDX17 was added to Intellectual disability syndromic and non-syndromic. Sources: Literature
Mode of inheritance for gene: DDX17 was set to MONOALLELIC, autosomal or pseudoautosomal, NOT imprinted
Publications for gene: DDX17 were set to https://www.medrxiv.org/search/DDX17
Phenotypes for gene: DDX17 were set to Neurodevelopmental disorder (MONDO#0700092), DDX17-related
Review for gene: DDX17 was set to GREEN
Added comment: https://www.medrxiv.org/search/DDX17 (pre-print)
11 patients with het de novo variants in DDX17 (5 NMD, 6 missense). Patient's phenotype included mild-moderate intellectual disability, delayed speech and language development and global developmental delay. 64% had dysmorphic facial features. Some patients also have gross and fine motor delay, generalized hypotonia, stereotypy, and evidence of autism spectrum disorder.

Knockdown of Ddx17 in newborn mice showed impaired axon outgrowth and reduced axon outgrowth and branching was observed in primary cortical neurons in vitro. This result was replicated in Crispant Xenopus tadpoles, which had clear functional neural defects and showed an impaired neurobehavioral phenotype.
Sources: Literature
Intellectual disability syndromic and non-syndromic v0.3675 DDX11 Zornitza Stark Marked gene: DDX11 as ready
Intellectual disability syndromic and non-syndromic v0.3675 DDX11 Zornitza Stark Gene: ddx11 has been classified as Green List (High Evidence).
Intellectual disability syndromic and non-syndromic v0.3675 DDX11 Zornitza Stark Phenotypes for gene: DDX11 were changed from to Warsaw breakage syndrome, MIM# 613398; MONDO:0013252
Intellectual disability syndromic and non-syndromic v0.3674 DDX11 Zornitza Stark Publications for gene: DDX11 were set to
Intellectual disability syndromic and non-syndromic v0.3673 DDX11 Zornitza Stark Mode of inheritance for gene: DDX11 was changed from Unknown to BIALLELIC, autosomal or pseudoautosomal
Intellectual disability syndromic and non-syndromic v0.3672 DDX11 Zornitza Stark reviewed gene: DDX11: Rating: GREEN; Mode of pathogenicity: None; Publications: 20137776, 23033317, 30216658; Phenotypes: Warsaw breakage syndrome, MIM# 613398, MONDO:0013252; Mode of inheritance: BIALLELIC, autosomal or pseudoautosomal
Intellectual disability syndromic and non-syndromic v0.0 DDX11 Zornitza Stark gene: DDX11 was added
gene: DDX11 was added to Intellectual disability, syndromic and non-syndromic_GHQ. Sources: Expert Review Green,Genetic Health Queensland
Mode of inheritance for gene: DDX11 was set to Unknown