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Palmoplantar Keratoderma and Erythrokeratoderma v1.3 EGFR chirag patel Marked gene: EGFR as ready
Palmoplantar Keratoderma and Erythrokeratoderma v1.3 EGFR chirag patel Gene: egfr has been classified as Amber List (Moderate Evidence).
Palmoplantar Keratoderma and Erythrokeratoderma v1.3 EGFR chirag patel Classified gene: EGFR as Amber List (moderate evidence)
Palmoplantar Keratoderma and Erythrokeratoderma v1.3 EGFR chirag patel Gene: egfr has been classified as Amber List (Moderate Evidence).
Palmoplantar Keratoderma and Erythrokeratoderma v1.2 EGFR chirag patel gene: EGFR was added
gene: EGFR was added to Palmoplantar Keratoderma and Erythrokeratoderma. Sources: Literature
Mode of inheritance for gene: EGFR was set to MONOALLELIC, autosomal or pseudoautosomal, NOT imprinted
Publications for gene: EGFR were set to 41533385
Phenotypes for gene: EGFR were set to Wooly hair-palmoplantar keratoderma syndrome, MONDO:0014492; Acanthosis nigricans MONDO:0007035
Mode of pathogenicity for gene: EGFR was set to Other
Review for gene: EGFR was set to AMBER
Added comment: 3 unrelated individuals presenting with widespread acanthosis nigricans, woolly hair, palmoplantar keratoderma and pulmonary nodules (consistent with atypical adenomatous hyperplasia). They all had the same heterozygous variant in EGFR (p.L858R). Two were shown to be de novo, and one was in post‑zygotic mosaic state. Patient‑cell assays show increased EGFR‑signalling supporting a gain of function mechanism. Therapy with an EGFR inhibitor in the 2 patients with germline variants showed marked improvement in skin and lung manifestations.
Sources: Literature