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Intellectual disability syndromic and non-syndromic v1.626 SEC31A Zornitza Stark Publications for gene: SEC31A were set to 30464055; 40508110
Intellectual disability syndromic and non-syndromic v1.625 SEC31A Zornitza Stark Classified gene: SEC31A as Green List (high evidence)
Intellectual disability syndromic and non-syndromic v1.625 SEC31A Zornitza Stark Gene: sec31a has been classified as Green List (High Evidence).
Intellectual disability syndromic and non-syndromic v1.624 SEC31A Zornitza Stark edited their review of gene: SEC31A: Added comment: PMID 39725565: Reports another individual from unrelated family with a homozygous splice‑acceptor loss‑of‑function variant (c.14351G>A) presenting with lethal neurodevelopmental disorder, dysmorphic facial features, brain anomalies, and severe skeletal defects. RT‑PCR on patient and carrier parents blood samples shows exon 12 skipping and markedly reduced SEC31A transcript, supporting loss‑of‑function.

Functional data from PMID 30464055: knockdown SEC31A Drosophila had defective brains and early lethality. In line with SEC31A encoding one of the two coating layers comprising the Coat protein complex II (COP-II) complex, trafficking newly synthesised proteins from the endoplasmic reticulum (ER) to the Golgi, CRISPR/Cas9-mediated SEC31A null mutant cells demonstrated reduced viability through upregulation of ER-stress pathways.; Changed rating: GREEN; Changed publications: 30464055, 40508110, 39725565; Changed phenotypes: Halperin-Birk syndrome, MIM# 618651
Intellectual disability syndromic and non-syndromic v1.440 SEC31A Zornitza Stark Phenotypes for gene: SEC31A were changed from ?Neurodevelopmental disorder with spastic quadriplegia, optic atrophy, seizures, and structural brain anomalies, OMIM #618651 to Halperin-Birk syndrome, MIM# 618651
Intellectual disability syndromic and non-syndromic v1.439 SEC31A Zornitza Stark Publications for gene: SEC31A were set to 30464055
Intellectual disability syndromic and non-syndromic v1.438 Zornitza Stark Added reviews for gene SEC31A from panel Arthrogryposis
Intellectual disability syndromic and non-syndromic v0.1409 SEC31A Tiong Tan Marked gene: SEC31A as ready
Intellectual disability syndromic and non-syndromic v0.1409 SEC31A Tiong Tan Gene: sec31a has been classified as Amber List (Moderate Evidence).
Intellectual disability syndromic and non-syndromic v0.1409 SEC31A Tiong Tan Classified gene: SEC31A as Amber List (moderate evidence)
Intellectual disability syndromic and non-syndromic v0.1409 SEC31A Tiong Tan Gene: sec31a has been classified as Amber List (Moderate Evidence).
Intellectual disability syndromic and non-syndromic v0.1408 SEC31A Tiong Tan gene: SEC31A was added
gene: SEC31A was added to Intellectual disability, syndromic and non-syndromic_GHQ_VCGS. Sources: Literature
Mode of inheritance for gene: SEC31A was set to BIALLELIC, autosomal or pseudoautosomal
Publications for gene: SEC31A were set to 30464055
Phenotypes for gene: SEC31A were set to ?Neurodevelopmental disorder with spastic quadriplegia, optic atrophy, seizures, and structural brain anomalies, OMIM #618651
Review for gene: SEC31A was set to AMBER
Added comment: Single family with two affected sibs with functional data (drosophila)
Sources: Literature