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Intellectual disability syndromic and non-syndromic v2.46 ASTN1 Zornitza Stark Phenotypes for gene: ASTN1 were changed from to Neurodevelopmental disorder (MONDO:0700092), ASTN1-related
Intellectual disability syndromic and non-syndromic v2.45 ASTN1 Zornitza Stark Publications for gene: ASTN1 were set to 29706646; 27431290; 26539891
Intellectual disability syndromic and non-syndromic v2.44 ASTN1 Zornitza Stark edited their review of gene: ASTN1: Added comment: PMID 41544630 reports 18 individuals with NDDs from 12 unrelated families with bi-allelic, ultra-rare, predicted damaging variants in ASTN1. Clinical features ranged from mild to profound developmental delay or intellectual disability +/- autism, ADHD, and epilepsy. Other recurrent abnormalities included dysmorphic facial features, hypotonia, spasticity, and ataxia. The neuroradiographic phenotype ranged from normal to mild (a thin corpus callosum and cerebellar dysgenesis), to severe (polymicrogyria and lissencephaly).; Changed publications: 41544630, 29706646, 27431290, 26539891; Changed phenotypes: Neurodevelopmental disorder (MONDO:0700092), ASTN1-related
Intellectual disability syndromic and non-syndromic v2.0 STN1 Gene migrated from ENSG00000107960 to ENSG00000107960 (gene set migration)
Intellectual disability syndromic and non-syndromic v0.6905 STN1 Zornitza Stark Marked gene: STN1 as ready
Intellectual disability syndromic and non-syndromic v0.6905 STN1 Zornitza Stark Gene: stn1 has been classified as Amber List (Moderate Evidence).
Intellectual disability syndromic and non-syndromic v0.6905 STN1 Zornitza Stark Phenotypes for gene: STN1 were changed from cerebral calcification; premature ageing; bone marrow failure; retinal telangiactasia; hepatic fibrosis to Cerebroretinal microangiopathy with calcification and cysts 2, MIM#617341
Intellectual disability syndromic and non-syndromic v0.3132 STN1 Sue White Classified gene: STN1 as Amber List (moderate evidence)
Intellectual disability syndromic and non-syndromic v0.3132 STN1 Sue White Gene: stn1 has been classified as Amber List (Moderate Evidence).
Intellectual disability syndromic and non-syndromic v0.3131 STN1 Sue White gene: STN1 was added
gene: STN1 was added to Intellectual disability syndromic and non-syndromic. Sources: Literature
Mode of inheritance for gene: STN1 was set to BIALLELIC, autosomal or pseudoautosomal
Publications for gene: STN1 were set to 32627942; 27432940
Phenotypes for gene: STN1 were set to cerebral calcification; premature ageing; bone marrow failure; retinal telangiactasia; hepatic fibrosis
Penetrance for gene: STN1 were set to Complete
Added comment: 3 unrelated patients reported with Coats-plus syndrome. Developmental delay noted in two.
Sources: Literature
Intellectual disability syndromic and non-syndromic v0.801 ASTN1 Zornitza Stark Marked gene: ASTN1 as ready
Intellectual disability syndromic and non-syndromic v0.801 ASTN1 Zornitza Stark Gene: astn1 has been classified as Green List (High Evidence).
Intellectual disability syndromic and non-syndromic v0.801 ASTN1 Zornitza Stark Classified gene: ASTN1 as Green List (high evidence)
Intellectual disability syndromic and non-syndromic v0.801 ASTN1 Zornitza Stark Gene: astn1 has been classified as Green List (High Evidence).
Intellectual disability syndromic and non-syndromic v0.3 ASTN1 Zornitza Stark gene: ASTN1 was added
gene: ASTN1 was added to Intellectual disability, syndromic and non-syndromic_GHQ. Sources: Expert list
Mode of inheritance for gene: ASTN1 was set to BIALLELIC, autosomal or pseudoautosomal
Publications for gene: ASTN1 were set to 29706646; 27431290; 26539891
Review for gene: ASTN1 was set to GREEN
gene: ASTN1 was marked as current diagnostic
Added comment: Three families reported as part of large cohorts albeit proposing multiple novel candidate genes with minimal detail and no functional validation.
Sources: Expert list