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Intellectual disability syndromic and non-syndromic v1.555 UNC13A Zornitza Stark Phenotypes for gene: UNC13A were changed from neurodevelopmental disorder MONDO#0700092, UNC13A-related; Neurodevelopmental disorder with hypotonia, epilepsy, and absent speech, MIM# 621455 to Neurodevelopmental disorder with speech delay, movement abnormalities, and seizures, MIM# 621456; Neurodevelopmental disorder with hypotonia, epilepsy, and absent speech, MIM# 621455
Intellectual disability syndromic and non-syndromic v1.554 UNC13A Zornitza Stark edited their review of gene: UNC13A: Changed phenotypes: Neurodevelopmental disorder with speech delay, movement abnormalities, and seizures, MIM# 621456, Neurodevelopmental disorder with hypotonia, epilepsy, and absent speech, MIM# 621455
Intellectual disability syndromic and non-syndromic v1.554 UNC13A Zornitza Stark Phenotypes for gene: UNC13A were changed from Congenital myasthenia; dyskinesia; autism; developmental delay; neurodevelopmental disorder MONDO#0700092, UNC13A-related to neurodevelopmental disorder MONDO#0700092, UNC13A-related; Neurodevelopmental disorder with hypotonia, epilepsy, and absent speech, MIM# 621455
Intellectual disability syndromic and non-syndromic v1.553 UNC13A Zornitza Stark Publications for gene: UNC13A were set to 27648472; 28192369
Intellectual disability syndromic and non-syndromic v1.552 UNC13A Zornitza Stark edited their review of gene: UNC13A: Changed publications: 27648472, 28192369, 41125872
Intellectual disability syndromic and non-syndromic v1.552 UNC13A Zornitza Stark edited their review of gene: UNC13A: Changed rating: GREEN
Intellectual disability syndromic and non-syndromic v1.552 UNC13A Zornitza Stark edited their review of gene: UNC13A: Added comment: PMID 41125872 reports 48 individuals with neurodevelopmental disorders and UNC13A variants. Of these, 20 classified as pathogenic. Of these 6 individuals had biallelic variants and presented with severe-to-profound GDD or intellectual disability, hypotonia and seizures of different types (largely controllable with medication) or death in early childhood caused by respiratory failure after pneumonia in one case. Mechanism for this subgroup is LoF with carrier parents unaffected.

A second group of 13 patients (21 months to 32 years old) harboured pathogenic, heterozygous de novo missense variants with multiple substitutions at amino acids 808, 811 and 814 (hinge region). They presented with variable degrees of GDD, hypotonia, seizures of different types (mainly refractory to treatment) and typically exhibited ataxia, tremor or dyskinetic movements rarely observed in other patients.

Also a family identified with at least four affected members across two generations (4 years to 35 years old) harbouring a pathogenic heterozygous missense variant (C587F) that caused learning difficulties to mild–moderate intellectual disability as well as controlled seizures.

Three different types of mechanism of pathogenicity proposed.; Changed phenotypes: neurodevelopmental disorder MONDO#0700092, UNC13A-related, Neurodevelopmental disorder with hypotonia, epilepsy, and absent speech, MIM# 621455
Intellectual disability syndromic and non-syndromic v0.5229 UNC13A Ain Roesley Phenotypes for gene: UNC13A were changed from Congenital myasthenia; dyskinesia; autism; developmental delay to Congenital myasthenia; dyskinesia; autism; developmental delay; neurodevelopmental disorder MONDO#0700092, UNC13A-related
Intellectual disability syndromic and non-syndromic v0.5229 UNC13A Ain Roesley Classified gene: UNC13A as Green List (high evidence)
Intellectual disability syndromic and non-syndromic v0.5229 UNC13A Ain Roesley Gene: unc13a has been classified as Green List (High Evidence).
Intellectual disability syndromic and non-syndromic v0.5228 UNC13A Ain Roesley reviewed gene: UNC13A: Rating: GREEN; Mode of pathogenicity: None; Publications: ; Phenotypes: neurodevelopmental disorder MONDO#0700092, UNC13A-related; Mode of inheritance: MONOALLELIC, autosomal or pseudoautosomal, NOT imprinted; Current diagnostic: yes
Intellectual disability syndromic and non-syndromic v0.2134 UNC13A Zornitza Stark Marked gene: UNC13A as ready
Intellectual disability syndromic and non-syndromic v0.2134 UNC13A Zornitza Stark Gene: unc13a has been classified as Red List (Low Evidence).
Intellectual disability syndromic and non-syndromic v0.2134 UNC13A Zornitza Stark Publications for gene: UNC13A were set to
Intellectual disability syndromic and non-syndromic v0.2129 UNC13A Zornitza Stark Phenotypes for gene: UNC13A were changed from to Congenital myasthenia; dyskinesia; autism; developmental delay
Intellectual disability syndromic and non-syndromic v0.2128 UNC13A Zornitza Stark Mode of inheritance for gene: UNC13A was changed from Unknown to BOTH monoallelic and biallelic, autosomal or pseudoautosomal
Intellectual disability syndromic and non-syndromic v0.2127 UNC13A Zornitza Stark Classified gene: UNC13A as Red List (low evidence)
Intellectual disability syndromic and non-syndromic v0.2127 UNC13A Zornitza Stark Gene: unc13a has been classified as Red List (Low Evidence).
Intellectual disability syndromic and non-syndromic v0.2126 UNC13A Zornitza Stark reviewed gene: UNC13A: Rating: RED; Mode of pathogenicity: None; Publications: 27648472, 28192369; Phenotypes: Congenital myasthenia, dyskinesia, autism, developmental delay; Mode of inheritance: BOTH monoallelic and biallelic, autosomal or pseudoautosomal
Intellectual disability syndromic and non-syndromic v0.0 UNC13A Zornitza Stark gene: UNC13A was added
gene: UNC13A was added to Intellectual disability, syndromic and non-syndromic_GHQ. Sources: Expert Review Green,Genetic Health Queensland
Mode of inheritance for gene: UNC13A was set to Unknown